TY - JOUR
T1 - Recurrent idiopathic pulmonary hemosiderosis after long-term remission presented with Sjogren's syndrome
T2 - Idiopathic no more?
AU - Yanagihara, Toyoshi
AU - Yamamoto, Yuzo
AU - Hamada, Naoki
AU - Suzuki, Kunihiro
AU - Ogata-Suetsugu, Saiko
AU - Harada, Eiji
AU - Tagawa, Tetsuzo
AU - Fujiwara, Minako
AU - Hashisako, Mikiko
AU - Fukuoka, Junya
AU - Nakanishi, Yoichi
N1 - Publisher Copyright:
© 2018 The Authors
PY - 2018/1/1
Y1 - 2018/1/1
N2 - We report a case of recurrent idiopathic pulmonary hemosiderosis after a long-term remission presented with Sjögren's syndrome. The patient was diagnosed with IPH due to repeated pneumonia and blood sputum in his childhood. He was admitted to our hospital due to exertional dyspnea and dry cough with bilateral ground-glass opacity in chest computed tomography at the age of 32. Video-assisted thoracoscopic surgery was performed and the specimens showed nonspecific interstitial pneumonia pattern with diffuse, chronic alveolar hemorrhage, suggesting recurrence of IPH. He was also diagnosed with Sjögren's syndrome. Further immunological studies will reveal the pathogenesis of IPH.
AB - We report a case of recurrent idiopathic pulmonary hemosiderosis after a long-term remission presented with Sjögren's syndrome. The patient was diagnosed with IPH due to repeated pneumonia and blood sputum in his childhood. He was admitted to our hospital due to exertional dyspnea and dry cough with bilateral ground-glass opacity in chest computed tomography at the age of 32. Video-assisted thoracoscopic surgery was performed and the specimens showed nonspecific interstitial pneumonia pattern with diffuse, chronic alveolar hemorrhage, suggesting recurrence of IPH. He was also diagnosed with Sjögren's syndrome. Further immunological studies will reveal the pathogenesis of IPH.
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U2 - 10.1016/j.rmcr.2018.06.013
DO - 10.1016/j.rmcr.2018.06.013
M3 - Article
AN - SCOPUS:85049351819
SN - 2213-0071
VL - 25
SP - 68
EP - 72
JO - Respiratory Medicine Case Reports
JF - Respiratory Medicine Case Reports
ER -